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Case Report

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Renal agenesis with ureterocele, duplicated megaureter and translocation of seminal vesicle: a case report and review of the literature

  • Jae Joon Park1
  • Woong Bin Kim2
  • Kwang Woo Lee2
  • Jun Mo Kim2
  • Young Ho Kim2
  • Ahrim Moon3
  • Jae Heon Kim1
  • Si Hyun Kim4
  • Sang Wook Lee2

1Department of Urology, Soonchunhyang University Seoul Hospital, Soonchunhyang University Medical College, 04401 Seoul, Republic of Korea

2Department of Urology, Soonchunhyang University Bucheon Hospital, Soonchunhyang University School of Medicine, 14584 Bucheon, Republic of Korea

3Department of Pathology, Soonchunhyang University Bucheon Hospital, Soonchunhyang University School of Medicine, 14584 Bucheon, Republic of Korea

4Department of Urology, Soonchunhyang University Cheonan Hospital, Soonchunhyang University School of Medicine, 31151 Cheonan, Republic of Korea

DOI: 10.31083/jomh.2021.088

Submitted: 19 April 2021 Accepted: 10 June 2021

Online publish date: 06 August 2021

*Corresponding Author(s): Sang Wook Lee E-mail: bartol@schmc.ac.kr

PDF (3.42 MB)

Abstract

Background: Renal agenesis is a congenital malformation that occurs due to the inhibition of metanephric blastema induction due to a decrease in ureteric bud activity. Although renal agenesis is not very rare, unilateral renal agenesis with ureterocele occurs rarely, and the coexistance of unilateral renal agenesis, ureterocele, and blind ended proximal ureter is very rare. Recently, we experienced a case of left renal agenesis with huge ureterocele, blind ended proximal ureter, and duplicated ureter on Computed tomography (CT) of a 17-year-old man who visited our emergency department with hematuria. Ureterocelectomy and nephrectomy were performed, and a translocation of seminal vesicle was also observed. This case is a very rare case, so we judged that it may be helpful in making treatment decisions in similar cases later.

Case summary: A 17-year-old man without specific medical history visited our emergency department with hematuria and voiding difficulty. CT showed left ectopic kidney, megaureter and the blind ended proximal ureter. After ureterocelectomy and nephrectomy, pathological examination revealed seminal vesicles in the periphery of the kidney. After one year, the patient has no complications and no complaining symptoms complaints without any abnormal finding of follow up imaging test.

Conclusions: This case report focuses on the treatment of renal agenesis with ureterocele, blind ended proximal ureter, duplicated megaureter and translocation of seminal vesicle. This rare case of treatment will be helpful in the determination of treatment for similar cases in the future. To establish standard treatment, data accumulation and well-designed studies are required.

Keywords

Urogenital abnormalities; Renal agenesis; Ureterocele; Seminal vesicles; Case report

Cite and Share

Jae Joon Park,Woong Bin Kim,Kwang Woo Lee,Jun Mo Kim,Young Ho Kim,Ahrim Moon,Jae Heon Kim,Si Hyun Kim,Sang Wook Lee. Renal agenesis with ureterocele, duplicated megaureter and translocation of seminal vesicle: a case report and review of the literature. Journal of Men's Health. 2021.doi:10.31083/jomh.2021.088.

References

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